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Pediatric case of persistent hiccups associated with hypertrophic olivary degeneration.

Authors
  • Arıcan, Pınar1
  • Öztekin, Özgür2
  • Çavuşoğlu, Dilek3
  • Yılmaz, Sema Bozkaya1
  • Ersen, Atilla1
  • Dündar, Nihal Olgaç4
  • Gençpınar, Pınar4
  • 1 Departments of Pediatric Neurology, İzmir Tepecik Education and Research Hospital, İzmir, Turkey. , (Turkey)
  • 2 Departments of Radiology, İzmir Tepecik Education and Research Hospital, İzmir, Turkey. , (Turkey)
  • 3 Department of Pediatric, Neurology, Afyon Kocatepe University, Afyon, Turkey. , (Turkey)
  • 4 Department of Pediatric Neurology, İzmir Katip Çelebi University, İzmir, Turkey. , (Turkey)
Type
Published Article
Journal
The Turkish Journal of Pediatrics
Publisher
The Turkish Journal of Pediatrics
Publication Date
Jan 01, 2020
Volume
62
Issue
2
Pages
343–346
Identifiers
DOI: 10.24953/turkjped.2020.02.025
PMID: 32419431
Source
Medline
Keywords
Language
English
License
Unknown

Abstract

Hypertrophic olivary degeneration (HOD) is a rare degenerative disorder that is thought to occur subsequent to a disruption of the dentate-rubro-olivary pathway. We report a pediatric case of unilateral HOD presented with persistent hiccups and palatal tremor. Radiological examination of diaphragm was normal considering ultrasound and chest x-ray. On T2WI (weighted images) and Fluid Attenuated Inversion Recovery (FLAIR) images, hyperintense enlargement of the right inferior olivary nucleus was seen. No abnormal enhancement was detected on post-contrast scans and no evidence of restricted diffusion was seen. Susceptibility weighted imaging (SWI) sequences revealed a chronic hemorrhage involving the medulla oblongata and cerebellum. Cranial magnetic resonance imaging (MRI) findings were consistent with unilateral HOD. Palatal tremor and dentate-rubral tremor are frequent presentation of HOD, however to our knowledge persistent hiccups had not yet been reported in children with HOD. We highlight a pediatric case of unilateral HOD, which presented with persistent hiccups. Awareness of clinical and radiological findings of HOD is important to avoid misinterpretation as a mass lesion, an ischemic event, or a demyelinating disease and provide adequate management.

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